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Japanese

RECURRENT PONTINE HEMORRHAGE ASSOCIATED WITH PERSISTENT PRIMITIVE TRIGEMINAL ARTERY AND FACIAL ANGIOMA Satoshi Miyahara 1 , Hideho Ohta 1 , Tosuke Takaki 1 , Yukichi Yonemasu 1 , Kiyoshi Yokota 2 1Department of Neurosurgery, Neurological Institute, Kyushu University 2Department of Pediatrics, Faculty of Medicine, Kyushu University pp.685-689
Published Date 1977/6/1
DOI https://doi.org/10.11477/mf.1406204091
  • Abstract
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The authors reported a case with recurrent pon-tine hemorrhage and concomitant facial angiomaand persistent primitive trigeminal artery. Thepatient, a 5-year-old boy, was well until the ageof 3 years when he was first noted to have stag-gering gait which was followed by facial paresisand hearing difficulty on the right. A mass lesionin the mid-pons on the right side was suggestedby brain scan, vertebral angiography and pneumo-encephalography. In addition, a right carotid an-giogram showed a persistent primitive trigeminalartery. No vascular abnormality such as aneurysm,arterio-venous malformation or carvenous angiomawas found in angiograms.

Under the diagnosis of pontine tumor, subocci-pital craniectomy was performed and a hemorrhagicsoftening was found in the right facial colliculusof the pons. The lesion was partially cystic andwas evacuated. No neoplastic or anomalous vasculartissue was found on the histological examinationof the tissue in the cyst.

He did well with a slight residual paresis for oneyear after surgery and then an acute exacerbationoccurred with Foville's alternating facialhemiplegia,dysarthria and dysphagia. No vascular anomalywas disclosed by repeated vertebral angiography.Yet, the findings at the previous operation and thecourse strongly suggested a recurrence of pontinehemorrhage. Neurological symptoms improved andthe patient was discharged with moderate residualalternating hemiparesis.

Reports on cases with persistent primitive trige-minal artery were reviewed with special referenceto associated vascular anomalies, and possible causeof pontine hemorrhage was discussed referring thereports on pontine vascular lesions.

It was presumed that the pontine hemorrhage inthis patient was caused by a vascular anomaly whichmay be related to the persistent primitive trige-minal artery and facial angioma as a neurocutaneousvascular developmental disorder, and the clinicalsignificance of facial angioma was emphasized.


Copyright © 1977, Igaku-Shoin Ltd. All rights reserved.

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電子版ISSN 2185-405X 印刷版ISSN 0006-8969 医学書院

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