両眼に発症した輪部デルモイドの1例

A case of limbal dermoid in both eyes

要約　目的：全身合併症がなく，両眼に発症した輪部デルモイドの症例の報告。症例：17歳女性が30か月前に両眼の輪部デルモイドと診断され，治療のため受診した。両眼に強度近視があり，矯正視力は右1.0，左1.5であった。右角膜の下方に径6mm，左角膜の下耳側に径7mmの楕円形で黄白色の隆起性腫瘤があった。両眼とも腫瘤に毛髪が数本あり，輪部デルモイドと診断した。全身麻酔下で両眼の腫瘤を摘出し，1個の新鮮角膜から採取した移植片で両眼に表層角膜移植術を行った。病理所見からデルモイドと診断した。術後矯正視力は右1.5，左1.2である。結論：全身合併症がない症例に，輪部デルモイドが両眼に発症することがある。本例では1個の新鮮角膜から両眼に表層角膜移植術を行うことができた。

Abstract.　Purpose：To report a case of limbal dermoid in both eyes. Case and Findings：A 17-year-old female presented with limbal dermoid in both eyes that had been diagnosed 30 months before. She had no systemic disorders. Both eyes had myopia of about 8 diopters. Corrected visual acuity was 1.0 right and 1.5 left. Both eyes showed an ovoid protruded tumor at the limbus. It was 6 mm across in the right eye and located at 6 o'clock posision. It was 7 mm across in the left eye located at 5 o'clock position. A few hairs were protruding from the tumor in both eyes,leading to the tentative diagnosis of limbal dermoid. Both eyes were treated by resection of tumor and lamellar keratoplasty using one fresh donor eye. The resected tumor was diagnosed with dermoid cyst histopathologically. She is doing well with corrected visual acuity of 1.5 and 1.2 respectively. Conclusion：This case illustrates that dermoid cyst may involve both eyes in a person without systemic disorders.