頭蓋内capillary hemangiomaの1例

Intracranial Capillary Hemangioma : A Case Report

I．はじめに

　Capillary hemangiomaは，一般に乳児の頭部や頸部の皮膚，口腔粘膜によくみられ^1,6），成長とともに自然に消退することが多い疾患である^{3，5,10,14）}．Capillary hemangiomaの中枢神経系での発生は稀であり，脊髄や馬尾神経での発生が散見されるが^7-9,11,12），頭蓋内での発生は少なく，また腫瘤としての報告は稀である．

　われわれは頭蓋内圧亢進症状にて発症した中頭蓋窩capillary hemangiomaの1例を経験したので，文献的考察を加えて報告する．

Capillary hemangiomas are the most common tumor of the neck and head in children. Intracranial capil-lary hemangioma without generalized neuro-cutaneous hemangiomatosis is extremely rare, with only onereport in the literature. We report a case of intracranial capillary hemangioma originating from the tempor-al base.

An 8-year-old boy presented with a severe headache and nausea. A CT scan showed a low-density areain the left temporal lobe and an iso-density mass at the temporal base. This mass was enhanced by con-trast medium. The mass lesion appeared as an iso-intensity area on T1-weighted MR images and as a high-intensity area on T2-weighted MR images, and the mass was enhanced almost uniformly by gadolinium-diethylene triaminepenta-acetic acid.

Cerebral angiography showed abnormal staining fed by the anterior temporal artery. An operation wasperformed, and all of the tumor with the dura attached was removed. The histological diagnosis was capil-lary hemangioma. The tumor consisted of a proliferation of capillary vessels lined by a single layer of en-dothelial cells.

In this paper, we review the clinical features, neuro-imaging findings and proposed etiology of capillary hemangioma.